Hereditary Spastic Paraplegia (HSP) - Dr. Ayman Nashashibi


Hereditary Spastic Paraplegia (HSP) - Dr. Ayman Nashashibi


Dr. Ayman NashashibiFamilial Spastic Paraparesis or Hereditary Spastic Paraplegia (HSP), is identified is a group of hereditary, degenerative, neurological disorders that primarily affect the upper motor neurons, where the upper motor neurons and the spinal cord transmit signals to the lower motor neurons as a mean to carry commands to the muscles.

In the case of HSP, upper motor neurons gradually degenerate, causing the muscles to stop receive the correct commands, causing increased muscle stiffness known as “spasticity”

Figure 1 Schematic diagram of the corticospinal tract emphasizing its descent through the CNS. Although most fibers decussate in the caudal medulla, a minority of fibers descend uncrossed as the ventral corticospinal tract (not shown).
illustration courtesy of Semantic Scholar

Prevalence

Hereditary spastic paraplegia has been reported in nearly every country with an estimated frequency ranging from 0.5 to 12 people per 100,000, but there isn’t an accurate data.  However, based on the most recent study by the Norwegian study rate of 7.4/100,000 of population has been estimated, without any reporting to gender involved in the study, although male patients were found to be significantly higher in number.

Average age of symptom onset is 24 years old. There is also juvenile onset HSP which can show up in children of any age and tends to be associated with more severe symptoms.

Symptoms

While the general feature of HSP is progressive fatigue and stiffness of the legs, the symptoms slowly progress so that at some point, patients with HSP may need assistance of a cane, walker, or wheelchair. Other reported symptoms may occur, including:

        Babinski's sign 
        epilepsy 
        hyperactive reflexes
        impaired vision
        ataxia
        Dementia
        urinary incontinence
        deafness
        difficulty with balance
        cognitive impairment
        peripheral neuropathy


Prognosis

The prognosis for individuals with HSP varies where some patients are very disabled while others are with mild disability. However, the majority of individuals with uncomplicated HSP live a normal life.


Hereditary factors

Most patients with HSP have inherited an abnormal gene from one of their parents, but in other cases, there have been reports attributed to causes when a child is conceived.
However, about 70-80% of cases of Hereditary spastic paraplegia result from autosomal dominant inheritance, and the remainder from autosomal recessive inheritance. 

Treatment

Currently, there is no cure for HSP nor a way to reverse it or pause it. However, many patients reported great benefits with foot surgery where tendons are relocated, to fitness and focused treatment from neurophysiotherapists for range of motion exercises and muscle strength. 
Treatments reported to have relieved of day-to-day activities have also been successful and include:

        Ankle-foot orthosis (a lower leg brace) can limit foot drop
        Muscle relaxants such as baclofen and tizanidine and botulinum 
        Antiepileptic and antinociceptive drugs such as Gabapentin leading to reduced neurotransmitter release and attenuation of postsynaptic excitability
        Betaine and Folinic Acid: 
        Hydrotherapy: the effect of hydrotherapy treatment in improving locomotor function in patients with late-onset HSP was evaluated in a small, uncontrolled trial, where 9 patients underwent a 10-week course /45 min per session of hydrotherapy, where significant pre- vs. post-therapy differences were observed 
         Physical therapy to maintain muscle strength and range motion.
        Botox Injections relieve spasticity
        Dorsal Rhizotomy can be used to relieve spasticity in cerebral palsy, but has also been tried in HSP


Conclusion
There is no general outlook for patients with HSP, as some patients are very disabled and need a wheelchair, while others only have a mild disability and do not need any walking aid.

Generally, most patients with HSP live a normal active life, even if they have to rely on a wheelchair.

HSP does not usually affect life expectancy.


Support Groups
National Organization for Rare Disorders (NORD) (https://rarediseases.org/)
Spastic Paraplegia Foundation (https://sp-foundation.org/)


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